TBX5 Chromosome 12

T-box transcription factor 5
183 variants 183 Health Risk

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What This Gene Does
This gene is a member of a phylogenetically conserved family of genes that share a common DNA-binding domain, the T-box. T-box genes encode transcription factors involved in the regulation of developmental processes. This gene is closely linked to related family member T-box 3 (ulnar mammary syndrome) on human chromosome 12. The encoded protein may play a role in heart development and specification of limb identity. Mutations in this gene have been associated with Holt-Oram syndrome, a developmental disorder affecting the heart and upper limbs. Several transcript variants encoding different isoforms have been described for this gene. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
T-box transcription factors
Locus Type
gene with protein product
Location
12q24.21
Ensembl
ENSG00000089225
Associated Conditions (15)
Aortic valve disease 2
Cardiovascular phenotype
Holt-Oram syndrome
TBX5-related disorder
Familial atrioventricular septal defect
Congenital heart disease (variable)
6 conditions
Heart
malformation of
Atrial septal defect
ostium secundum type
Ventricular septal defect
Mitral regurgitation
Atrial septal defect 1
Primary dilated cardiomyopathy
Key Variants
RS1396124456
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS141609745
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS143068551
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
Health Risk
RS146908258
Conflicting classifications of pathogenicity
Cardiovascular phenotype, Cardiovascular phenotype
Health Risk
RS1565941576
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS1871568678
Conflicting classifications of pathogenicity
Aortic valve disease 2, Aortic valve disease 2
Health Risk
RS1871830806
Conflicting classifications of pathogenicity
Aortic valve disease 2, Aortic valve disease 2
Health Risk
RS200382742
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Aortic valve disease 2, Cardiovascular phenotype
Health Risk
RS200461617
Conflicting classifications of pathogenicity
Cardiovascular phenotype, Holt-Oram syndrome, Aortic valve disease 2
Health Risk
RS201152128
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS201637366
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
Health Risk
RS2136397905
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
All Variants (183)
RSID Category Clinical Significance Conditions
RS1396124456 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS141609745 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
RS143068551 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
RS146908258 Health Risk Conflicting classifications of pathogenicity Cardiovascular phenotype, Cardiovascular phenotype
RS1565941576 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
RS1871568678 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Aortic valve disease 2
RS1871830806 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Aortic valve disease 2
RS200382742 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Aortic valve disease 2, Cardiovascular phenotype
RS200461617 Health Risk Conflicting classifications of pathogenicity Cardiovascular phenotype, Holt-Oram syndrome, Aortic valve disease 2
RS201152128 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS201637366 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
RS2136397905 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS2540471405 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Aortic valve disease 2
RS2540475446 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Holt-Oram syndrome
RS368311885 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS530882236 Health Risk Conflicting classifications of pathogenicity Cardiovascular phenotype, Aortic valve disease 2, Cardiovascular phenotype
RS556197042 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS577615373 Health Risk Conflicting classifications of pathogenicity Cardiovascular phenotype, Aortic valve disease 2, Cardiovascular phenotype
RS745378130 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
RS758752836 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS759976245 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS761952835 Health Risk Conflicting classifications of pathogenicity Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS763827720 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
RS771400478 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Aortic valve disease 2, Holt-Oram syndrome
RS775748269 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Aortic valve disease 2, Cardiovascular phenotype
RS886044059 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Holt-Oram syndrome
RS886048997 Health Risk Conflicting classifications of pathogenicity Holt-Oram syndrome, Cardiovascular phenotype, Holt-Oram syndrome
RS1057519050 Health Risk Likely pathogenic Familial atrioventricular septal defect, Familial atrioventricular septal defect
RS1131691460 Health Risk Likely pathogenic
RS1131691932 Health Risk Likely pathogenic
RS1555223294 Health Risk Likely pathogenic Congenital heart disease (variable), Congenital heart disease (variable), Congenital heart disease (variable)
RS1555226301 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1555226575 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1555226584 Health Risk Likely pathogenic
RS1565935314 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1565935426 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1565935458 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1565940841 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1565941072 Health Risk Likely pathogenic Aortic valve disease 2, Aortic valve disease 2
RS1565941579 Health Risk Likely pathogenic 6 conditions, Holt-Oram syndrome, 6 conditions
RS1870765797 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1870766319 Health Risk Likely pathogenic
RS1871328960 Health Risk Likely pathogenic Aortic valve disease 2, Aortic valve disease 2
RS2136411098 Health Risk Likely pathogenic Aortic valve disease 2, TBX5-related disorder, Aortic valve disease 2
RS2136416601 Health Risk Likely pathogenic Aortic valve disease 2, Aortic valve disease 2
RS2540424549 Health Risk Likely pathogenic Cardiovascular phenotype, Aortic valve disease 2, Cardiovascular phenotype
RS2540425164 Health Risk Likely pathogenic Cardiovascular phenotype, Cardiovascular phenotype
RS2540457891 Health Risk Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS2540467182 Health Risk Likely pathogenic Aortic valve disease 2, Aortic valve disease 2
RS2540471325 Health Risk Likely pathogenic
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