TBX5 Chromosome 12

T-box transcription factor 5
183 variants 183 Health Risk

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What This Gene Does
This gene is a member of a phylogenetically conserved family of genes that share a common DNA-binding domain, the T-box. T-box genes encode transcription factors involved in the regulation of developmental processes. This gene is closely linked to related family member T-box 3 (ulnar mammary syndrome) on human chromosome 12. The encoded protein may play a role in heart development and specification of limb identity. Mutations in this gene have been associated with Holt-Oram syndrome, a developmental disorder affecting the heart and upper limbs. Several transcript variants encoding different isoforms have been described for this gene. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
T-box transcription factors
Locus Type
gene with protein product
Location
12q24.21
Ensembl
ENSG00000089225
Associated Conditions (15)
Aortic valve disease 2
Cardiovascular phenotype
Holt-Oram syndrome
TBX5-related disorder
Familial atrioventricular septal defect
Congenital heart disease (variable)
6 conditions
Heart
malformation of
Atrial septal defect
ostium secundum type
Ventricular septal defect
Mitral regurgitation
Atrial septal defect 1
Primary dilated cardiomyopathy
Key Variants
RS1396124456
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS141609745
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS143068551
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
Health Risk
RS146908258
Conflicting classifications of pathogenicity
Cardiovascular phenotype, Cardiovascular phenotype
Health Risk
RS1565941576
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS1871568678
Conflicting classifications of pathogenicity
Aortic valve disease 2, Aortic valve disease 2
Health Risk
RS1871830806
Conflicting classifications of pathogenicity
Aortic valve disease 2, Aortic valve disease 2
Health Risk
RS200382742
Conflicting classifications of pathogenicity
Holt-Oram syndrome, Aortic valve disease 2, Cardiovascular phenotype
Health Risk
RS200461617
Conflicting classifications of pathogenicity
Cardiovascular phenotype, Holt-Oram syndrome, Aortic valve disease 2
Health Risk
RS201152128
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
RS201637366
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Holt-Oram syndrome
Health Risk
RS2136397905
Conflicting classifications of pathogenicity
Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
Health Risk
All Variants (183)
RSID Category Clinical Significance Conditions
RS2540436280 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS2540436320 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS2540457334 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS2540466994 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS2540467152 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS2540471436 Health Risk Pathogenic Cardiovascular phenotype, Cardiovascular phenotype
RS2540471519 Health Risk Pathogenic
RS2540472661 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS2540475443 Health Risk Pathogenic
RS2540477662 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS483353129 Health Risk Pathogenic
RS756049331 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS765204502 Health Risk Pathogenic Holt-Oram syndrome, Aortic valve disease 2, Holt-Oram syndrome
RS773397553 Health Risk Pathogenic
RS863223773 Health Risk Pathogenic
RS863223777 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS863223783 Health Risk Pathogenic
RS863223784 Health Risk Pathogenic
RS863223785 Health Risk Pathogenic
RS863223786 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS863223788 Health Risk Pathogenic Aortic valve disease 2, Holt-Oram syndrome, TBX5-related disorder
RS867641094 Health Risk Pathogenic
RS878853750 Health Risk Pathogenic Aortic valve disease 2, Aortic valve disease 2
RS886041247 Health Risk Pathogenic Aortic valve disease 2, Holt-Oram syndrome, Cardiovascular phenotype
RS886041606 Health Risk Pathogenic
RS903933027 Health Risk Pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1555226581 Health Risk Pathogenic/Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS1593881162 Health Risk Pathogenic/Likely pathogenic Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS1869545659 Health Risk Pathogenic/Likely pathogenic Aortic valve disease 2, Holt-Oram syndrome, Aortic valve disease 2
RS2136373205 Health Risk Pathogenic/Likely pathogenic Aortic valve disease 2, Cardiovascular phenotype, Aortic valve disease 2
RS2136421421 Health Risk Pathogenic/Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome
RS767197919 Health Risk Pathogenic/Likely pathogenic Holt-Oram syndrome, Holt-Oram syndrome, Cardiovascular phenotype
RS863223776 Health Risk Pathogenic/Likely pathogenic TBX5-related disorder, Holt-Oram syndrome, Aortic valve disease 2
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