NUS1 Chromosome 6

NUS1 dehydrodolichyl diphosphate synthase subunit
66 variants 66 Health Risk

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What This Gene Does
This gene encodes a type I single transmembrane domain receptor, which is a subunit of cis-prenyltransferase, and serves as a specific receptor for the neural and cardiovascular regulator Nogo-B. The encoded protein is essential for dolichol synthesis and protein glycosylation. This gene is highly expressed in non-small cell lung carcinomas as well as estrogen receptor-alpha positive breast cancer cells where it promotes epithelial mesenchymal transition. This gene is associated with the poor prognosis of human hepatocellular carcinoma patients. Naturally occurring mutations in this gene cause a congenital disorder of glycosylation and are associated with epilepsy. A knockout of the orthologous gene in mice causes embryonic lethality before day 6.5. Pseudogenes of this gene have been defined on chromosomes 13 and X. [provided by RefSeq, May 2017]
Gene Info
Gene Group
Dehydrodolichyl diphosphate synthase
Locus Type
gene with protein product
Location
6q22.1
Ensembl
ENSG00000153989
Associated Conditions (9)
Congenital disorder of glycosylation
type IAA
Inborn genetic diseases
Intellectual disability
autosomal dominant 55
with seizures
NUS1-related disorder
Congenital bilateral perisylvian syndrome
NUS1-related epilepsy-myoclonus-ataxia syndrome
Key Variants
RS1023259853
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
Health Risk
RS1460197813
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
Health Risk
RS146171115
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
Health Risk
RS150646335
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Intellectual disability
Health Risk
RS2114687510
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Intellectual disability
Health Risk
RS557867164
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
Health Risk
RS753713015
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
Health Risk
RS761121795
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
Health Risk
RS772319851
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
Health Risk
RS886037858
Conflicting classifications of pathogenicity
Congenital disorder of glycosylation, type IAA, Intellectual disability
Health Risk
RS1582477100
Likely pathogenic
Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
Health Risk
RS1772961410
Likely pathogenic
Health Risk
All Variants (66)
RSID Category Clinical Significance Conditions
RS1023259853 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
RS1460197813 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
RS146171115 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS150646335 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Intellectual disability
RS2114687510 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Intellectual disability
RS557867164 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Inborn genetic diseases
RS753713015 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS761121795 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS772319851 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS886037858 Health Risk Conflicting classifications of pathogenicity Congenital disorder of glycosylation, type IAA, Intellectual disability
RS1582477100 Health Risk Likely pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS1772961410 Health Risk Likely pathogenic
RS1773283124 Health Risk Likely pathogenic
RS2114674308 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2114687537 Health Risk Likely pathogenic
RS2114693876 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2481981792 Health Risk Likely pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2481982183 Health Risk Likely pathogenic
RS2481983096 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2481983597 Health Risk Likely pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2481983903 Health Risk Likely pathogenic NUS1-related disorder, NUS1-related disorder
RS2481983991 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2482014062 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2482015846 Health Risk Likely pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2482016013 Health Risk Likely pathogenic Congenital bilateral perisylvian syndrome, Congenital bilateral perisylvian syndrome
RS2482016210 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2482032232 Health Risk Likely pathogenic
RS2482037745 Health Risk Likely pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS746614172 Health Risk Likely pathogenic NUS1-related disorder, NUS1-related disorder
RS1407880094 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1449400618 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS1554200722 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1554202698 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1582461023 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS1582461039 Health Risk Pathogenic Inborn genetic diseases, Inborn genetic diseases
RS1582461235 Health Risk Pathogenic
RS1582461267 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1772963498 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS1773264138 Health Risk Pathogenic Inborn genetic diseases, Inborn genetic diseases
RS1773264504 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1773460199 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS1773460504 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2114674305 Health Risk Pathogenic
RS2114674385 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2114674415 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2114693926 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2481982381 Health Risk Pathogenic Intellectual disability, autosomal dominant 55, with seizures
RS2481982600 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2481982643 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
RS2481982674 Health Risk Pathogenic Congenital disorder of glycosylation, type IAA, Congenital disorder of glycosylation
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