SPAST Chromosome 2

Spastin
499 variants 499 Health Risk

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What This Gene Does
This gene encodes a member of the AAA (ATPases associated with a variety of cellular activities) protein family. Members of this protein family share an ATPase domain and have roles in diverse cellular processes including membrane trafficking, intracellular motility, organelle biogenesis, protein folding, and proteolysis. The use of alternative translational initiation sites in this gene results in a single transcript variant that can produce isoforms that differ in the length of their N-terminus and which thereby differ in the efficiency of their export from the nucleus to the cytoplasm. In addition, alternative splicing results in multiple transcript variants that encode isoforms that differ in other protein regions as well. One isoform of this gene has been shown to be a microtubule-severing enzyme that regulates microtubule abundance, mobility, and plus-end distribution. Mutations in this gene cause the most frequent form of autosomal dominant spastic paraplegia 4. [provided by RefSeq, May 2018]
Gene Info
Gene Group
AAA ATPases
Locus Type
gene with protein product
Location
2p22.3
Ensembl
ENSG00000021574
Associated Conditions (21)
Hereditary spastic paraplegia 4
Cerebral palsy
Hereditary spastic paraplegia
SPAST-related disorder
Inborn genetic diseases
Spastic diplegia
Spastic paraplegia
Spastic ataxia
Spastic paraparesis
Spasticity
Hereditary spastic paraplegia 2
Tics
SPAST-related spastic paraplegia
Melanoma
Abnormal central motor function
Fatigue
Abnormal myelination
Seizure
Tip-toe gait
Pes valgus
+1 more conditions
Key Variants
RS121908515
Benign/Likely benign; other; risk factor
Hereditary spastic paraplegia 4, Cerebral palsy, Hereditary spastic paraplegia
Health Risk
RS1057519108
Conflicting classifications of pathogenicity
Health Risk
RS1060499939
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia
Health Risk
RS1060502228
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, SPAST-related disorder, Hereditary spastic paraplegia 4
Health Risk
RS1060502231
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
Health Risk
RS1131691972
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
Health Risk
RS1162493574
Conflicting classifications of pathogenicity
Inborn genetic diseases, Hereditary spastic paraplegia 4, Inborn genetic diseases
Health Risk
RS121908517
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia, Hereditary spastic paraplegia 4
Health Risk
RS138146982
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
Health Risk
RS140094231
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
Health Risk
RS1403480959
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
Health Risk
RS142053576
Conflicting classifications of pathogenicity
Hereditary spastic paraplegia 4, Inborn genetic diseases, Spastic diplegia
Health Risk
All Variants (499)
RSID Category Clinical Significance Conditions
RS878854991 Health Risk Likely pathogenic Hereditary spastic paraplegia 4, Inborn genetic diseases, Abnormal central motor function
RS1036039694 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1057517974 Health Risk Pathogenic
RS1057518880 Health Risk Pathogenic Spastic paraplegia, Spastic paraplegia
RS1057519181 Health Risk Pathogenic Hereditary spastic paraplegia 4, Inborn genetic diseases, Hereditary spastic paraplegia 4
RS1057521135 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1060502229 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1060502230 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1131691977 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1189374970 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1218081251 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS121908509 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS121908510 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS121908514 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia, Hereditary spastic paraplegia 4
RS121908516 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS121908518 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia
RS121908519 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1233469782 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1268625226 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1315245986 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1318536893 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1365753930 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1377020559 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1384312757 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1410418105 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1421791559 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1462628095 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1471030618 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1485703744 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553314868 Health Risk Pathogenic
RS1553314880 Health Risk Pathogenic
RS1553314896 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553314902 Health Risk Pathogenic Hereditary spastic paraplegia, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia
RS1553314948 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553314951 Health Risk Pathogenic
RS1553314978 Health Risk Pathogenic Spastic paraplegia, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553314979 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315169 Health Risk Pathogenic
RS1553315181 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315188 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315236 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315240 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315318 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia, Hereditary spastic paraplegia 4
RS1553315321 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315323 Health Risk Pathogenic
RS1553315329 Health Risk Pathogenic Fatigue, Abnormal myelination, Seizure
RS1553315336 Health Risk Pathogenic
RS1553315345 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315350 Health Risk Pathogenic Hereditary spastic paraplegia 4, Hereditary spastic paraplegia 4
RS1553315352 Health Risk Pathogenic
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