PKHD1 Chromosome 6

PKHD1 ciliary IPT domain containing fibrocystin/polyductin
1463 variants 1463 Health Risk

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What This Gene Does
The protein encoded by this gene is predicted to have a single transmembrane (TM)-spanning domain and multiple copies of an immunoglobulin-like plexin-transcription-factor domain. Alternative splicing results in two transcript variants encoding different isoforms. Other alternatively spliced transcripts have been described, but the full length sequences have not been determined. Several of these transcripts are predicted to encode truncated products which lack the TM and may be secreted. Mutations in this gene cause autosomal recessive polycystic kidney disease, also known as polycystic kidney and hepatic disease-1. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
IPT domain containing
Locus Type
gene with protein product
Location
6p12.3-p12.2
Ensembl
ENSG00000170927
Associated Conditions (38)
Autosomal recessive polycystic kidney disease
PKHD1-related disorder
Inborn genetic diseases
Polycystic kidney disease 4
Polycystic kidney disease
See cases
Incidental Discovery
Autosomal dominant polycystic liver disease
Renal cyst
adult type
Caroli disease
Kidney failure
Nonpapillary renal cell carcinoma
Sarcoma
Biliary tract abnormality
Hereditary disease
Gastric cancer
Familial cancer of breast
Autosomal dominant polycystic kidney disease
Cystic renal disease
+18 more conditions
Key Variants
RS1042054004
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
Health Risk
RS1054774956
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
Health Risk
RS112030234
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Inborn genetic diseases, PKHD1-related disorder
Health Risk
RS112249812
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
Health Risk
RS113402912
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
Health Risk
RS113562492
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Polycystic kidney disease, Autosomal recessive polycystic kidney disease
Health Risk
RS114237522
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
Health Risk
RS116809571
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
Health Risk
RS1204544455
Conflicting classifications of pathogenicity
Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4
Health Risk
RS1207597891
Conflicting classifications of pathogenicity
Polycystic kidney disease 4, Polycystic kidney disease 4
Health Risk
RS1229139298
Conflicting classifications of pathogenicity
Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4
Health Risk
RS1271940495
Conflicting classifications of pathogenicity
Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
Health Risk
All Variants (1463)
RSID Category Clinical Significance Conditions
RS141093030 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS141103838 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, PKHD1-related disorder
RS141177165 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS1412045164 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS141360909 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS1413693039 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS141574387 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS141622697 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS141638079 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, Autosomal recessive polycystic kidney disease
RS141790557 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS142205860 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS1424171216 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
RS142526715 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal dominant polycystic liver disease, PKHD1-related disorder
RS142678486 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS142855690 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS142896856 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal dominant polycystic liver disease
RS142922408 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS143616240 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, PKHD1-related disorder
RS143682303 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
RS143737660 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Inborn genetic diseases
RS143979330 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease, PKHD1-related disorder
RS144025892 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS144042993 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, PKHD1-related disorder
RS144106341 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS144365187 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS144455663 Health Risk Conflicting classifications of pathogenicity Polycystic kidney disease 4, Inborn genetic diseases, PKHD1-related disorder
RS144673879 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, Autosomal recessive polycystic kidney disease
RS144841026 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS144905283 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS145141656 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Inborn genetic diseases
RS145163993 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, Polycystic kidney disease 4
RS145219220 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, PKHD1-related disorder
RS1453006216 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease 4, Autosomal recessive polycystic kidney disease
RS145651593 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, PKHD1-related disorder
RS145745489 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, Autosomal recessive polycystic kidney disease
RS145789167 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, Polycystic kidney disease 4
RS145815264 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
RS145886657 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS145960781 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS145979687 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS146083613 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
RS146102132 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Inborn genetic diseases, PKHD1-related disorder
RS146224907 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
RS146468152 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS146519878 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Polycystic kidney disease, Autosomal dominant polycystic liver disease
RS146531432 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS146745096 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Polycystic kidney disease 4
RS146789444 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Inborn genetic diseases
RS147051900 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, PKHD1-related disorder, Autosomal recessive polycystic kidney disease
RS147051973 Health Risk Conflicting classifications of pathogenicity Autosomal recessive polycystic kidney disease, Autosomal recessive polycystic kidney disease
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