OPA1 Chromosome 3

OPA1 mitochondrial dynamin like GTPase
348 variants 348 Health Risk

Upload your DNA to see your personal genotypes for variants in OPA1.

What This Gene Does
The protein encoded by this gene is a nuclear-encoded mitochondrial protein with similarity to dynamin-related GTPases. The encoded protein localizes to the inner mitochondrial membrane and helps regulate mitochondrial stability and energy output. This protein also sequesters cytochrome c. Mutations in this gene have been associated with optic atrophy type 1, which is a dominantly inherited optic neuropathy resulting in progressive loss of visual acuity, leading in many cases to legal blindness. [provided by RefSeq, Aug 2017]
Gene Info
Gene Group
Dynamin superfamily
Locus Type
gene with protein product
Location
3q29
Ensembl
ENSG00000198836
Associated Conditions (33)
Optic atrophy with or without deafness
ophthalmoplegia
myopathy
ataxia
and neuropathy
Autosomal dominant optic atrophy classic form
Inborn genetic diseases
Abortive cerebellar ataxia
Mitochondrial DNA depletion syndrome 14 (cardioencephalomyopathic type)
Glaucoma
normal tension
susceptibility to
Optic nerve hypoplasia
OPA1-related disorder
Optic atrophy
Childhood onset hearing loss
Auditory neuropathy spectrum disorder
Retinal dystrophy
Abnormal brain morphology
Auditory neuropathy
+13 more conditions
Key Variants
All Variants (348)
RSID Category Clinical Significance Conditions
RS794727405 Health Risk Pathogenic Optic atrophy with or without deafness, ophthalmoplegia, myopathy
RS794727804 Health Risk Pathogenic Inborn genetic diseases, Autosomal dominant optic atrophy classic form, Stargardt disease
RS80356528 Health Risk Pathogenic Optic atrophy, Optic atrophy
RS80356529 Health Risk Pathogenic Optic atrophy with or without deafness, ophthalmoplegia, myopathy
RS80356531 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS863224127 Health Risk Pathogenic Optic atrophy, Optic atrophy
RS863224128 Health Risk Pathogenic
RS863224134 Health Risk Pathogenic Optic atrophy, Optic atrophy
RS863224141 Health Risk Pathogenic
RS863224142 Health Risk Pathogenic
RS863224143 Health Risk Pathogenic
RS869312995 Health Risk Pathogenic Mitochondrial DNA depletion syndrome 14 (cardioencephalomyopathic type), Mitochondrial DNA depletion syndrome 14 (cardioencephalomyopathic type)
RS879255510 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS879255511 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS879255512 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS879255513 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Optic atrophy with or without deafness, ophthalmoplegia
RS879255592 Health Risk Pathogenic Optic atrophy with or without deafness, ophthalmoplegia, myopathy
RS879255595 Health Risk Pathogenic Abortive cerebellar ataxia, Autosomal dominant optic atrophy classic form, Abortive cerebellar ataxia
RS886041318 Health Risk Pathogenic OPA1-related disorder, Autosomal dominant optic atrophy classic form, OPA1-related disorder
RS886041438 Health Risk Pathogenic
RS886043136 Health Risk Pathogenic
RS886043317 Health Risk Pathogenic
RS921531106 Health Risk Pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS1048376563 Health Risk Pathogenic/Likely pathogenic
RS121908375 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Optic atrophy with or without deafness, ophthalmoplegia
RS1319065221 Health Risk Pathogenic/Likely pathogenic
RS1553877864 Health Risk Pathogenic/Likely pathogenic Mitochondrial disease, Mitochondrial disease
RS1577162868 Health Risk Pathogenic/Likely pathogenic Optic atrophy with or without deafness, ophthalmoplegia, myopathy
RS1577228080 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Neurodevelopmental disorder, Autosomal dominant optic atrophy classic form
RS1577242473 Health Risk Pathogenic/Likely pathogenic
RS1711518217 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Optic atrophy, Autosomal dominant optic atrophy classic form
RS1716524583 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, OPA1-related disorder, Optic atrophy
RS2109057450 Health Risk Pathogenic/Likely pathogenic
RS2109138909 Health Risk Pathogenic/Likely pathogenic Optic atrophy, Autosomal dominant optic atrophy classic form, Optic atrophy
RS2109460398 Health Risk Pathogenic/Likely pathogenic
RS2474599159 Health Risk Pathogenic/Likely pathogenic OPA1-related disorder, OPA1-related disorder
RS2474922093 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS2475167246 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS2475204678 Health Risk Pathogenic/Likely pathogenic Abortive cerebellar ataxia, Abortive cerebellar ataxia
RS747454971 Health Risk Pathogenic/Likely pathogenic Uterine corpus endometrial carcinoma, Uterine corpus endometrial carcinoma
RS754576717 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Autosomal dominant optic atrophy classic form
RS761460379 Health Risk Pathogenic/Likely pathogenic Retinal dystrophy, Autosomal dominant optic atrophy classic form, OPA1-related disorder
RS794727069 Health Risk Pathogenic/Likely pathogenic
RS80356530 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Abortive cerebellar ataxia, Mitochondrial disease
RS863224906 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, OPA1-related disorder, Optic atrophy
RS879255560 Health Risk Pathogenic/Likely pathogenic Autosomal dominant optic atrophy classic form, Optic atrophy, Autosomal dominant optic atrophy classic form
RS879255593 Health Risk Pathogenic/Likely pathogenic Abortive cerebellar ataxia, Retinal dystrophy, Abortive cerebellar ataxia
RS983041061 Health Risk Pathogenic/Likely pathogenic
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