OFD1 Chromosome X

OFD1 centriole and centriolar satellite protein
176 variants 176 Health Risk

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What This Gene Does
This gene is located on the X chromosome and encodes a centrosomal protein. A knockout mouse model has been used to study the effect of mutations in this gene. The mouse gene is also located on the X chromosome, however, unlike the human gene it is not subject to X inactivation. Mutations in this gene are associated with oral-facial-digital syndrome type I and Simpson-Golabi-Behmel syndrome type 2. Many pseudogenes have been identified; a single pseudogene is found on chromosome 5 while as many as fifteen have been found on the Y chromosome. [provided by RefSeq, Aug 2016]
Associated Conditions (31)
Joubert syndrome
Orofaciodigital syndrome I
Primary ciliary dyskinesia
OFD1-related disorder
Joubert syndrome 10
Retinitis pigmentosa 23
Simpson-Golabi-Behmel syndrome type 2
Nonpapillary renal cell carcinoma
History of neurodevelopmental disorder
Congenital anomaly of kidney and urinary tract
Malignant tumor of urinary bladder
Retinal dystrophy
Rare genetic intellectual disability
Cervical cancer
Intellectual disability
Cerebral arteriopathy
autosomal dominant
with subcortical infarcts and leukoencephalopathy
type 1
Thyroid cancer
+11 more conditions
Key Variants
RS1191893961
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
Health Risk
RS1254987046
Conflicting classifications of pathogenicity
OFD1-related disorder, Joubert syndrome, Orofaciodigital syndrome I
Health Risk
RS1260959326
Conflicting classifications of pathogenicity
Joubert syndrome 10, Joubert syndrome, Orofaciodigital syndrome I
Health Risk
RS1283023888
Conflicting classifications of pathogenicity
Orofaciodigital syndrome I, Joubert syndrome, Primary ciliary dyskinesia
Health Risk
RS1355239331
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
Health Risk
RS1374240720
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, OFD1-related disorder
Health Risk
RS139444990
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, OFD1-related disorder
Health Risk
RS146251034
Conflicting classifications of pathogenicity
Orofaciodigital syndrome I, Joubert syndrome, History of neurodevelopmental disorder
Health Risk
RS147114577
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
Health Risk
RS149473481
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
Health Risk
RS149790559
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Orofaciodigital syndrome I, Joubert syndrome
Health Risk
RS150560046
Conflicting classifications of pathogenicity
Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
Health Risk
All Variants (176)
RSID Category Clinical Significance Conditions
RS769469366 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
RS770614769 Health Risk Conflicting classifications of pathogenicity Orofaciodigital syndrome I, Joubert syndrome 10, Retinitis pigmentosa 23
RS771742424 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
RS775062213 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Primary ciliary dyskinesia
RS778349684 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Simpson-Golabi-Behmel syndrome type 2
RS780055525 Health Risk Conflicting classifications of pathogenicity Orofaciodigital syndrome I, Joubert syndrome, Primary ciliary dyskinesia
RS780064168 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome
RS781665189 Health Risk Conflicting classifications of pathogenicity Orofaciodigital syndrome I, Joubert syndrome, Retinal dystrophy
RS797045846 Health Risk Conflicting classifications of pathogenicity Orofaciodigital syndrome I, Joubert syndrome, Retinitis pigmentosa 23
RS797045847 Health Risk Conflicting classifications of pathogenicity Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS797045848 Health Risk Conflicting classifications of pathogenicity Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS863225213 Health Risk Conflicting classifications of pathogenicity Joubert syndrome 10, Orofaciodigital syndrome I, Joubert syndrome
RS912239987 Health Risk Conflicting classifications of pathogenicity Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome 10
RS1019055469 Health Risk Likely pathogenic Simpson-Golabi-Behmel syndrome type 2, Simpson-Golabi-Behmel syndrome type 2
RS1131691889 Health Risk Likely pathogenic Joubert syndrome 10, Joubert syndrome 10
RS1555900675 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1555900734 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1555901169 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1555902797 Health Risk Likely pathogenic
RS1555904480 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1555906316 Health Risk Likely pathogenic
RS1569102786 Health Risk Likely pathogenic Joubert syndrome, Orofaciodigital syndrome I, Thyroid cancer
RS1569145145 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1602826217 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1602904530 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS1602942625 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2047765952 Health Risk Likely pathogenic
RS2047796952 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2047909739 Health Risk Likely pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2047914412 Health Risk Likely pathogenic Joubert syndrome 10, Ventriculomegaly, Polymicrogyria
RS2048164566 Health Risk Likely pathogenic
RS2146913390 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2147016815 Health Risk Likely pathogenic Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome
RS2147060430 Health Risk Likely pathogenic Joubert syndrome 10, Joubert syndrome 10
RS2147060461 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2147086315 Health Risk Likely pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2518776413 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2518778078 Health Risk Likely pathogenic Orofaciodigital syndrome I, OFD1-related disorder, Orofaciodigital syndrome I
RS2518821166 Health Risk Likely pathogenic OFD1-related disorder, OFD1-related disorder
RS2518924222 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2518937760 Health Risk Likely pathogenic Orofaciodigital syndrome I, Orofaciodigital syndrome I
RS2518939102 Health Risk Likely pathogenic Joubert syndrome 10, Joubert syndrome 10
RS312262869 Health Risk Likely pathogenic Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome
RS750227810 Health Risk Likely pathogenic Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome
RS766872363 Health Risk Likely pathogenic Orofaciodigital syndrome I, Joubert syndrome, Orofaciodigital syndrome I
RS769923969 Health Risk Likely pathogenic Joubert syndrome, Orofaciodigital syndrome I, Joubert syndrome
RS770656547 Health Risk Likely pathogenic
RS797044917 Health Risk Likely pathogenic Inborn genetic diseases, Inborn genetic diseases
RS1057518526 Health Risk Pathogenic
RS1060500123 Health Risk Pathogenic Joubert syndrome, Orofaciodigital syndrome I, OFD1-related disorder
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