OBSCN Chromosome 1

Obscurin, cytoskeletal calmodulin and titin-interacting RhoGEF
90 variants 90 Health Risk

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What This Gene Does
The obscurin gene spans more than 150 kb, contains over 80 exons and encodes a protein of approximately 720 kDa. The encoded protein contains 68 Ig domains, 2 fibronectin domains, 1 calcium/calmodulin-binding domain, 1 RhoGEF domain with an associated PH domain, and 2 serine-threonine kinase domains. This protein belongs to the family of giant sacromeric signaling proteins that includes titin and nebulin, and may have a role in the organization of myofibrils during assembly and may mediate interactions between the sarcoplasmic reticulum and myofibrils. Alternatively spliced transcript variants encoding different isoforms have been identified. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
"Fibronectin type III domain containing|I-set domain containing|Dbl family Rho GEFs|Myosin light chain kinase family"
Locus Type
gene with protein product
Location
1q42.13
Ensembl
ENSG00000154358
Associated Conditions (8)
OBSCN-related disorder
Rhabdomyolysis
susceptibility to
1
Inborn genetic diseases
Short stature
Hearing loss
autosomal recessive 120
Key Variants
All Variants (90)
RSID Category Clinical Significance Conditions
RS1413609730 Health Risk Likely pathogenic
RS1480591236 Health Risk Likely pathogenic Short stature, Short stature
RS200849058 Health Risk Likely pathogenic Rhabdomyolysis, susceptibility to, 1
RS2531495848 Health Risk Likely pathogenic Rhabdomyolysis, susceptibility to, 1
RS2545712483 Health Risk Likely pathogenic OBSCN-related disorder, OBSCN-related disorder
RS2545765366 Health Risk Likely pathogenic
RS527810384 Health Risk Likely pathogenic
RS531159549 Health Risk Likely pathogenic
RS1029972302 Health Risk Pathogenic
RS1158912574 Health Risk Pathogenic
RS1206678898 Health Risk Pathogenic OBSCN-related disorder, OBSCN-related disorder
RS1290761535 Health Risk Pathogenic
RS1338686840 Health Risk Pathogenic
RS1357560938 Health Risk Pathogenic
RS1417203331 Health Risk Pathogenic
RS1429044506 Health Risk Pathogenic
RS1474373656 Health Risk Pathogenic
RS2046932510 Health Risk Pathogenic
RS2528397772 Health Risk Pathogenic
RS2531180833 Health Risk Pathogenic
RS2531516441 Health Risk Pathogenic
RS2531745043 Health Risk Pathogenic
RS2544971701 Health Risk Pathogenic
RS2544986066 Health Risk Pathogenic
RS2545162609 Health Risk Pathogenic
RS375527061 Health Risk Pathogenic
RS531253434 Health Risk Pathogenic Rhabdomyolysis, susceptibility to, 1
RS749025131 Health Risk Pathogenic Hearing loss, autosomal recessive 120, Hearing loss
RS752364658 Health Risk Pathogenic
RS755201622 Health Risk Pathogenic
RS758667776 Health Risk Pathogenic
RS761256819 Health Risk Pathogenic
RS770491191 Health Risk Pathogenic
RS781071008 Health Risk Pathogenic
RS869312933 Health Risk Pathogenic Inborn genetic diseases, Inborn genetic diseases
RS980884830 Health Risk Pathogenic
RS1322344930 Health Risk risk factor Rhabdomyolysis, susceptibility to, 1
RS2531580019 Health Risk risk factor Rhabdomyolysis, susceptibility to, 1
RS766814997 Health Risk risk factor Rhabdomyolysis, susceptibility to, 1
RS775772574 Health Risk risk factor Rhabdomyolysis, susceptibility to, 1
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