MOCOS Chromosome 18

Molybdenum cofactor sulfurase
30 variants 30 Health Risk

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What This Gene Does
This gene encodes an enzyme that sulfurates the molybdenum cofactor which is required for activation of the xanthine dehydrogenase (XDH) and aldehyde oxidase (AO) enzymes. XDH catalyzes the conversion of hypoxanthine to uric acid via xanthine, as well as the conversion of allopurinol to oxypurinol, and pyrazinamide to 5-hydroxy pyrazinamide. Mutations in this gene cause the metabolic disorder classical xanthinuria type II which is characterized by the loss of XDH/XO and AO enzyme activity, decreased levels of uric acid in the urine, increased levels of xanthine and hypoxanthine in the serum and urine, formation of xanthine stones in the urinary tract, and myositis due to tissue deposition of xanthine. [provided by RefSeq, Apr 2017]
Associated Conditions (3)
Xanthinuria type II
MOCOS-related disorder
Autism spectrum disorder
Key Variants
All Variants (30)
RSID Category Clinical Significance Conditions
RS1156588840 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS139002197 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, MOCOS-related disorder, Xanthinuria type II
RS144081367 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS144644128 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS200725272 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS2091346076 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS747252798 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS768710712 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS910676616 Health Risk Conflicting classifications of pathogenicity Xanthinuria type II, Xanthinuria type II
RS1164875023 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS1262090219 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS1318625944 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS1362463869 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS138341349 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS1424773596 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS2510968407 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS2510984845 Health Risk Likely pathogenic Xanthinuria type II, MOCOS-related disorder, Xanthinuria type II
RS2511387782 Health Risk Likely pathogenic Xanthinuria type II, Xanthinuria type II
RS2511390167 Health Risk Likely pathogenic MOCOS-related disorder, MOCOS-related disorder
RS142150953 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS1699077839 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS2091474513 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS2510966451 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS2510983262 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS2510984970 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS775406459 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS886037854 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS886037855 Health Risk Pathogenic Xanthinuria type II, Xanthinuria type II
RS750896617 Health Risk Pathogenic/Likely pathogenic Xanthinuria type II, Autism spectrum disorder, Xanthinuria type II
RS761752580 Health Risk Pathogenic/Likely pathogenic Xanthinuria type II, Xanthinuria type II
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