GUCY2D Chromosome 17

Guanylate cyclase 2D, retinal
236 variants 236 Health Risk

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What This Gene Does
This gene encodes a retina-specific guanylate cyclase, which is a member of the membrane guanylyl cyclase family. Like other membrane guanylyl cyclases, this enzyme has a hydrophobic amino-terminal signal sequence followed by a large extracellular domain, a single membrane spanning domain, a kinase homology domain, and a guanylyl cyclase catalytic domain. In contrast to other membrane guanylyl cyclases, this enzyme is not activated by natriuretic peptides. Mutations in this gene result in Leber congenital amaurosis and cone-rod dystrophy-6 diseases. [provided by RefSeq, Dec 2008]
Gene Info
Gene Group
Transmembrane guanylate cyclases
Locus Type
gene with protein product
Location
17p13.1
Ensembl
ENSG00000132518
Associated Conditions (28)
Leber congenital amaurosis 1
Cone-rod dystrophy 6
Inborn genetic diseases
GUCY2D-related disorder
Retinal dystrophy
Choroidal dystrophy
central areolar
1
Night blindness
congenital stationary
type1i
Cataract
Cone-rod dystrophy
Cone dystrophy
Leber congenital amaurosis
GUCY2D-related recessive retinopathy
Retinal disorder
Autosomal recessive optic atrophy
Congenital blindness
Early-onset retinal dystrophy
+8 more conditions
Key Variants
RS1064797217
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS1237783733
Conflicting classifications of pathogenicity
Inborn genetic diseases, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS138836357
Conflicting classifications of pathogenicity
Cone-rod dystrophy 6, Leber congenital amaurosis 1, GUCY2D-related disorder
Health Risk
RS141967896
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS1445892049
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS146849545
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS1478566225
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS148136213
Conflicting classifications of pathogenicity
Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS149866657
Conflicting classifications of pathogenicity
Retinal dystrophy, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS1975925973
Conflicting classifications of pathogenicity
Retinal dystrophy, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
RS1975935914
Conflicting classifications of pathogenicity
Cone-rod dystrophy, Retinal dystrophy, Cone-rod dystrophy
Health Risk
RS1975936032
Conflicting classifications of pathogenicity
Retinal dystrophy, Cone-rod dystrophy 6, Leber congenital amaurosis 1
Health Risk
All Variants (236)
RSID Category Clinical Significance Conditions
RS878853342 Health Risk Likely pathogenic Retinal dystrophy, Retinal dystrophy
RS931906767 Health Risk Likely pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis, Leber congenital amaurosis 1
RS1006935198 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Choroidal dystrophy
RS1168076308 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1195374954 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1200134985 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, GUCY2D-related disorder
RS1200884939 Health Risk Pathogenic Night blindness, congenital stationary, type1i
RS12602083 Health Risk Pathogenic
RS1275955653 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1290420698 Health Risk Pathogenic Leber congenital amaurosis 1, Night blindness, congenital stationary
RS1308509257 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1338490917 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Night blindness
RS1349155167 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1374426388 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1403798841 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1424348888 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1451359371 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1452774826 Health Risk Pathogenic Congenital blindness, Congenital blindness
RS1555635550 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1555635668 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1555635778 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1567956946 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1567961680 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Retinal dystrophy
RS1567961697 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Night blindness
RS1598146173 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, GUCY2D-related recessive retinopathy
RS1598146589 Health Risk Pathogenic Leber congenital amaurosis, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1598149187 Health Risk Pathogenic Leber congenital amaurosis, Leber congenital amaurosis
RS1598150539 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy
RS1975665345 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975665578 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1975675766 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975678842 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975693728 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1975751307 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975768901 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975890613 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975893449 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975911430 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1975923246 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975936949 Health Risk Pathogenic Night blindness, congenital stationary, type1i
RS1975937052 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1975943416 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1975943461 Health Risk Pathogenic Leber congenital amaurosis 1, Leber congenital amaurosis 1
RS1975955933 Health Risk Pathogenic Cone-rod dystrophy 6, Cone-rod dystrophy 6
RS1975957350 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1975957618 Health Risk Pathogenic Leber congenital amaurosis 1, Cone-rod dystrophy 6, Leber congenital amaurosis 1
RS1975959442 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1975964112 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
RS1975973086 Health Risk Pathogenic Early-onset retinal dystrophy, Early-onset retinal dystrophy
RS201587670 Health Risk Pathogenic Cone-rod dystrophy 6, Leber congenital amaurosis 1, Cone-rod dystrophy 6
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