FCHO1 Chromosome 19

FCH and mu domain containing endocytic adaptor 1
24 variants 24 Health Risk

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What This Gene Does
Enables AP-2 adaptor complex binding activity. Involved in several processes, including T cell receptor signaling pathway; clathrin coat assembly; and clathrin-dependent endocytosis. Located in cytosol; nucleoplasm; and plasma membrane. Is active in clathrin-coated pit. Implicated in primary immunodeficiency disease. [provided by Alliance of Genome Resources, Jul 2025]
Gene Info
Gene Group
F-BAR domain containing
Locus Type
gene with protein product
Location
19p13.11
Ensembl
ENSG00000130475
Associated Conditions (4)
Immunodeficiency 76
FCHO1-related disorder
Severe congenital neutropenia
Immunodeficiency with T and B cell lymphopenia
Key Variants
All Variants (24)
RSID Category Clinical Significance Conditions
RS139750085 Health Risk Conflicting classifications of pathogenicity
RS139967668 Health Risk Conflicting classifications of pathogenicity Immunodeficiency 76, Immunodeficiency 76
RS145154295 Health Risk Conflicting classifications of pathogenicity
RS186812006 Health Risk Conflicting classifications of pathogenicity
RS202047816 Health Risk Conflicting classifications of pathogenicity
RS748448687 Health Risk Conflicting classifications of pathogenicity
RS761640192 Health Risk Conflicting classifications of pathogenicity
RS2513631162 Health Risk Likely pathogenic FCHO1-related disorder, FCHO1-related disorder
RS753935822 Health Risk Likely pathogenic
RS772008992 Health Risk Likely pathogenic
RS1336566500 Health Risk Pathogenic Severe congenital neutropenia, Immunodeficiency with T and B cell lymphopenia, Severe congenital neutropenia
RS148410831 Health Risk Pathogenic
RS2083028943 Health Risk Pathogenic Immunodeficiency 76, Immunodeficiency 76
RS2086875746 Health Risk Pathogenic Severe congenital neutropenia, Immunodeficiency 76, Severe congenital neutropenia
RS2087831882 Health Risk Pathogenic Immunodeficiency 76, Immunodeficiency 76
RS2089298923 Health Risk Pathogenic Severe congenital neutropenia, Immunodeficiency 76, Severe congenital neutropenia
RS2091196149 Health Risk Pathogenic Severe congenital neutropenia, Severe congenital neutropenia
RS2093571190 Health Risk Pathogenic Severe congenital neutropenia, Immunodeficiency 76, Severe congenital neutropenia
RS2147209050 Health Risk Pathogenic
RS2147323888 Health Risk Pathogenic
RS2513888704 Health Risk Pathogenic
RS2514155878 Health Risk Pathogenic
RS2514358325 Health Risk Pathogenic
RS530286781 Health Risk Pathogenic Severe congenital neutropenia, Immunodeficiency 76, Severe congenital neutropenia
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