EPM2A Chromosome 6

EPM2A glucan phosphatase, laforin
63 variants 63 Health Risk

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What This Gene Does
This gene encodes a dual-specificity phosphatase and may be involved in the regulation of glycogen metabolism. The protein acts on complex carbohydrates to prevent glycogen hyperphosphorylation, thus avoiding the formation of insoluble aggregates. Loss-of-function mutations in this gene have been associated with Lafora disease, a rare, adult-onset recessive neurodegenerative disease, which results in myoclonus epilepsy and usually results in death several years after the onset of symptoms. The disease is characterized by the accumulation of insoluble particles called Lafora bodies, which are derived from glycogen. [provided by RefSeq, Jan 2018]
Gene Info
Gene Group
Atypical dual specificity phosphatases
Locus Type
gene with protein product
Location
6q24.3
Ensembl
ENSG00000112425
Associated Conditions (15)
Progressive myoclonic epilepsy
Inborn genetic diseases
Myoclonic epilepsy of Lafora 1
Lafora disease
EPM2A-related disorder
Intellectual disability
Severe global developmental delay
Cataract
Microcephaly
Myoclonic epilepsy
progressive
X-linked
Seizure
Abnormality of the nervous system
Self-limited epilepsy with centrotemporal spikes
Key Variants
RS1367012950
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
Health Risk
RS1386913118
Conflicting classifications of pathogenicity
Myoclonic epilepsy of Lafora 1, Lafora disease, Myoclonic epilepsy of Lafora 1
Health Risk
RS1387516050
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
Health Risk
RS1454552122
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
Health Risk
RS146321088
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Lafora disease, Inborn genetic diseases
Health Risk
RS147399860
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Intellectual disability, Inborn genetic diseases
Health Risk
RS150452237
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Severe global developmental delay, Cataract
Health Risk
RS1582935082
Conflicting classifications of pathogenicity
Myoclonic epilepsy, progressive, X-linked
Health Risk
RS2128649886
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
Health Risk
RS374043005
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Seizure, Inborn genetic diseases
Health Risk
RS547147183
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
Health Risk
RS571938170
Conflicting classifications of pathogenicity
Progressive myoclonic epilepsy, Inborn genetic diseases, EPM2A-related disorder
Health Risk
All Variants (63)
RSID Category Clinical Significance Conditions
RS1367012950 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
RS1386913118 Health Risk Conflicting classifications of pathogenicity Myoclonic epilepsy of Lafora 1, Lafora disease, Myoclonic epilepsy of Lafora 1
RS1387516050 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS1454552122 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS146321088 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Inborn genetic diseases
RS147399860 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Intellectual disability, Inborn genetic diseases
RS150452237 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Severe global developmental delay, Cataract
RS1582935082 Health Risk Conflicting classifications of pathogenicity Myoclonic epilepsy, progressive, X-linked
RS2128649886 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS374043005 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Seizure, Inborn genetic diseases
RS547147183 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
RS571938170 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, EPM2A-related disorder
RS587780938 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Lafora disease
RS749937487 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Lafora disease
RS761970395 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS763719276 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
RS776655093 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Inborn genetic diseases, Progressive myoclonic epilepsy
RS777308612 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS777767978 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS796052428 Health Risk Conflicting classifications of pathogenicity Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS1131691331 Health Risk Likely pathogenic Lafora disease, Lafora disease
RS1179064700 Health Risk Likely pathogenic Abnormality of the nervous system, Abnormality of the nervous system
RS1362231306 Health Risk Likely pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS1384780611 Health Risk Likely pathogenic Myoclonic epilepsy of Lafora 1, Myoclonic epilepsy of Lafora 1
RS1583155981 Health Risk Likely pathogenic
RS2534173440 Health Risk Likely pathogenic Myoclonic epilepsy of Lafora 1, Myoclonic epilepsy of Lafora 1
RS2534173846 Health Risk Likely pathogenic Myoclonic epilepsy of Lafora 1, Myoclonic epilepsy of Lafora 1
RS587776554 Health Risk Likely pathogenic Myoclonic epilepsy of Lafora 1, Lafora disease, Myoclonic epilepsy of Lafora 1
RS796052427 Health Risk Likely pathogenic Lafora disease, Lafora disease
RS796052434 Health Risk Likely pathogenic
RS1204045237 Health Risk Pathogenic Progressive myoclonic epilepsy, Lafora disease, Myoclonic epilepsy of Lafora 1
RS1361221383 Health Risk Pathogenic Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS1554263318 Health Risk Pathogenic
RS1554263320 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS1554263366 Health Risk Pathogenic Self-limited epilepsy with centrotemporal spikes, Self-limited epilepsy with centrotemporal spikes
RS1775923311 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS1776788274 Health Risk Pathogenic Lafora disease, Lafora disease
RS1776791266 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS1776817138 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS1780901751 Health Risk Pathogenic Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS2128555980 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS2128614455 Health Risk Pathogenic Myoclonic epilepsy of Lafora 1, Myoclonic epilepsy of Lafora 1
RS2533594050 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS2533595059 Health Risk Pathogenic Inborn genetic diseases, Inborn genetic diseases
RS2533595069 Health Risk Pathogenic Inborn genetic diseases, Inborn genetic diseases
RS2534171587 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS2534174818 Health Risk Pathogenic Progressive myoclonic epilepsy, Progressive myoclonic epilepsy
RS587776553 Health Risk Pathogenic Myoclonic epilepsy of Lafora 1, Lafora disease, Myoclonic epilepsy of Lafora 1
RS750988816 Health Risk Pathogenic Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
RS780648601 Health Risk Pathogenic Progressive myoclonic epilepsy, Lafora disease, Progressive myoclonic epilepsy
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