DIAPH1 Chromosome 5

Diaphanous related formin 1
99 variants 99 Health Risk

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What This Gene Does
This gene is a homolog of the Drosophila diaphanous gene, and has been linked to autosomal dominant, fully penetrant, nonsyndromic sensorineural progressive low-frequency hearing loss. Actin polymerization involves proteins known to interact with diaphanous protein in Drosophila and mouse. It has therefore been speculated that this gene may have a role in the regulation of actin polymerization in hair cells of the inner ear. Alternatively spliced transcript variants encoding distinct isoforms have been found for this gene. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
"Armadillo like helical domain containing|Formins"
Locus Type
gene with protein product
Location
5q31.3
Ensembl
ENSG00000131504
Associated Conditions (19)
Autosomal dominant nonsyndromic hearing loss 1
Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
Inborn genetic diseases
DIAPH1-related disorder
Familial pancreatic carcinoma
Colorectal cancer
See cases
Beta-D-mannosidosis
Macrothrombocytopenia
Hearing impairment
Neonatal seizure
Pendred syndrome
Auditory neuropathy spectrum disorder
Deafness
Rare genetic deafness
Global developmental delay
Microcephaly
Epilepsy
Failure to thrive
Key Variants
RS1284785470
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
Health Risk
RS1335130331
Conflicting classifications of pathogenicity
Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
Health Risk
RS1356596414
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
Health Risk
RS1455848656
Conflicting classifications of pathogenicity
Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
Health Risk
RS1474809251
Conflicting classifications of pathogenicity
Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Inborn genetic diseases
Health Risk
RS148686869
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Autosomal dominant nonsyndromic hearing loss 1
Health Risk
RS1596330487
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
Health Risk
RS182139018
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, DIAPH1-related disorder
Health Risk
RS189809247
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, DIAPH1-related disorder
Health Risk
RS190481949
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Inborn genetic diseases
Health Risk
RS193036129
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Familial pancreatic carcinoma
Health Risk
RS199749212
Conflicting classifications of pathogenicity
Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, DIAPH1-related disorder
Health Risk
All Variants (99)
RSID Category Clinical Significance Conditions
RS773243948 Health Risk Conflicting classifications of pathogenicity Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Inborn genetic diseases
RS773440011 Health Risk Conflicting classifications of pathogenicity Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS777195456 Health Risk Conflicting classifications of pathogenicity Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Inborn genetic diseases
RS781577050 Health Risk Conflicting classifications of pathogenicity Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Beta-D-mannosidosis
RS886060034 Health Risk Conflicting classifications of pathogenicity Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1596335566 Health Risk Likely pathogenic Macrothrombocytopenia, Hearing impairment, Macrothrombocytopenia
RS1596339533 Health Risk Likely pathogenic Autosomal dominant nonsyndromic hearing loss 1, Autosomal dominant nonsyndromic hearing loss 1
RS1596393434 Health Risk Likely pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1596421912 Health Risk Likely pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2099887720 Health Risk Likely pathogenic Neonatal seizure, Neonatal seizure
RS2099887774 Health Risk Likely pathogenic
RS2099896905 Health Risk Likely pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2154596304 Health Risk Likely pathogenic Pendred syndrome, Pendred syndrome
RS2154596416 Health Risk Likely pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2154596613 Health Risk Likely pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2513627688 Health Risk Likely pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2513764771 Health Risk Likely pathogenic Auditory neuropathy spectrum disorder, Auditory neuropathy spectrum disorder
RS758562288 Health Risk Likely pathogenic DIAPH1-related disorder, DIAPH1-related disorder
RS763349669 Health Risk Likely pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS774337037 Health Risk Likely pathogenic
RS1057524293 Health Risk Pathogenic
RS1064794044 Health Risk Pathogenic
RS1064797096 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Autosomal dominant nonsyndromic hearing loss 1
RS1331356644 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS1378791199 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1455361577 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1461242879 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1476157529 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS1554201397 Health Risk Pathogenic
RS2099888710 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2099895754 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2154596284 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2154596448 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2154596461 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2154597562 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS2513621738 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2513738067 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2513746067 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS2513850974 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS369494682 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, DIAPH1-related disorder
RS753100456 Health Risk Pathogenic Neonatal seizure, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Neonatal seizure
RS755174598 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS766545876 Health Risk Pathogenic Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS771360300 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS863225242 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS863225243 Health Risk Pathogenic Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Deafness, Autosomal dominant nonsyndromic hearing loss 1
RS876657776 Health Risk Pathogenic Rare genetic deafness, Autosomal dominant nonsyndromic hearing loss 1, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome
RS1235751512 Health Risk Pathogenic/Likely pathogenic Hearing impairment, Progressive microcephaly-seizures-cortical blindness-developmental delay syndrome, Autosomal dominant nonsyndromic hearing loss 1
RS730882242 Health Risk Pathogenic/Likely pathogenic Global developmental delay, Microcephaly, Epilepsy
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