DBT Chromosome 1

Dihydrolipoamide branched chain transacylase E2
162 variants 162 Health Risk

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What This Gene Does
The branched-chain alpha-keto acid dehydrogenase complex (BCKD) is an inner-mitochondrial enzyme complex involved in the breakdown of the branched-chain amino acids isoleucine, leucine, and valine. The BCKD complex is thought to be composed of a core of 24 transacylase (E2) subunits, and associated decarboxylase (E1), dehydrogenase (E3), and regulatory subunits. This gene encodes the transacylase (E2) subunit. Mutations in this gene result in maple syrup urine disease, type 2. Alternatively spliced transcript variants have been described, but their biological validity has not been determined. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
Branched chain alpha-keto acid dehydrogenase complex subunits
Locus Type
gene with protein product
Location
1p21.2
Ensembl
ENSG00000137992
Associated Conditions (6)
Maple syrup urine disease
Maple syrup urine disease type 1A
DBT-related disorder
Maple syrup urine disease type 2
Inborn genetic diseases
See cases
Key Variants
RS1131691488
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
Health Risk
RS113842781
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
Health Risk
RS138796800
Conflicting classifications of pathogenicity
Maple syrup urine disease, DBT-related disorder, Maple syrup urine disease
Health Risk
RS1449113689
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease type 2, Maple syrup urine disease type 1A
Health Risk
RS148571335
Conflicting classifications of pathogenicity
Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
Health Risk
RS1663813561
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease
Health Risk
RS199954954
Conflicting classifications of pathogenicity
Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
Health Risk
RS200339376
Conflicting classifications of pathogenicity
Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
Health Risk
RS201318480
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease
Health Risk
RS201714436
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease
Health Risk
RS398123658
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease
Health Risk
RS398123662
Conflicting classifications of pathogenicity
Maple syrup urine disease, Maple syrup urine disease
Health Risk
All Variants (162)
RSID Category Clinical Significance Conditions
RS1131691488 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
RS113842781 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
RS138796800 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, DBT-related disorder, Maple syrup urine disease
RS1449113689 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 2, Maple syrup urine disease type 1A
RS148571335 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
RS1663813561 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS199954954 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
RS200339376 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
RS201318480 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS201714436 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS398123658 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS398123662 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS398123669 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 2, Maple syrup urine disease
RS398123672 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS533707792 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
RS727503896 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
RS749693779 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Inborn genetic diseases, Maple syrup urine disease
RS75525811 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, DBT-related disorder, Maple syrup urine disease
RS759312184 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS770981889 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 2, Maple syrup urine disease
RS772490888 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
RS776490043 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS79292123 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS794727856 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS886044964 Health Risk Conflicting classifications of pathogenicity Maple syrup urine disease, Maple syrup urine disease
RS1064795955 Health Risk Likely pathogenic
RS1176555925 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease, Maple syrup urine disease
RS1271011315 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1310427311 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1342553753 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease, Maple syrup urine disease
RS1553228653 Health Risk Likely pathogenic Maple syrup urine disease type 1A, Maple syrup urine disease type 1A
RS1553229661 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease type 1A, Maple syrup urine disease
RS1553231037 Health Risk Likely pathogenic Maple syrup urine disease type 1A, Maple syrup urine disease type 1A
RS1553232188 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease, Maple syrup urine disease
RS1553232197 Health Risk Likely pathogenic Maple syrup urine disease type 1A, Maple syrup urine disease type 1A
RS1553233152 Health Risk Likely pathogenic Maple syrup urine disease type 1A, Maple syrup urine disease type 1A
RS1557943881 Health Risk Likely pathogenic Maple syrup urine disease type 1A, Maple syrup urine disease, Maple syrup urine disease
RS1557956678 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1661796496 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1661797008 Health Risk Likely pathogenic Maple syrup urine disease type 2, Maple syrup urine disease type 2
RS1661797765 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1663520073 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1663522846 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1663814011 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1663814241 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS1663814857 Health Risk Likely pathogenic Maple syrup urine disease type 2, Maple syrup urine disease type 2
RS1664173086 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS2100779875 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease type 2, Maple syrup urine disease
RS2100799417 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
RS2100844517 Health Risk Likely pathogenic Maple syrup urine disease, Maple syrup urine disease
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