CEP290 Chromosome 12

Centrosomal protein 290
892 variants 892 Health Risk

Upload your DNA to see your personal genotypes for variants in CEP290.

What This Gene Does
This gene encodes a protein with 13 putative coiled-coil domains, a region with homology to SMC chromosome segregation ATPases, six KID motifs, three tropomyosin homology domains and an ATP/GTP binding site motif A. The protein is localized to the centrosome and cilia and has sites for N-glycosylation, tyrosine sulfation, phosphorylation, N-myristoylation, and amidation. Mutations in this gene have been associated with Joubert syndrome and nephronophthisis and the presence of antibodies against this protein is associated with several forms of cancer. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
MKS complex
Locus Type
gene with protein product
Location
12q21.32
Ensembl
ENSG00000198707
Associated Conditions (61)
Nephronophthisis
Meckel-Gruber syndrome
Joubert syndrome
Senior-Loken syndrome 6
Joubert syndrome 5
Leber congenital amaurosis 10
Meckel syndrome
type 4
Bardet-Biedl syndrome 14
Leber congenital amaurosis
Hepatocellular carcinoma
Inborn genetic diseases
CEP290-related disorder
Intellectual disability
Retinal dystrophy
Retinitis pigmentosa
Kidney disorder
CEP290-related ciliopathy
Joubert syndrome 1
Atypical hemolytic-uremic syndrome
+41 more conditions
Key Variants
RS1036812157
Conflicting classifications of pathogenicity
Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
Health Risk
RS11104729
Conflicting classifications of pathogenicity
Bardet-Biedl syndrome 14, Joubert syndrome 5, Leber congenital amaurosis 10
Health Risk
RS1159465602
Conflicting classifications of pathogenicity
Senior-Loken syndrome 6, Meckel syndrome, type 4
Health Risk
RS1165909730
Conflicting classifications of pathogenicity
Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
Health Risk
RS117370446
Conflicting classifications of pathogenicity
Meckel syndrome, type 4, Bardet-Biedl syndrome 14
Health Risk
RS117852025
Conflicting classifications of pathogenicity
Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
Health Risk
RS11836796
Conflicting classifications of pathogenicity
Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
Health Risk
RS1200834763
Conflicting classifications of pathogenicity
Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
Health Risk
RS1213124542
Conflicting classifications of pathogenicity
Retinal dystrophy, CEP290-related disorder, Retinal dystrophy
Health Risk
RS1301659851
Conflicting classifications of pathogenicity
Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
Health Risk
RS1330745435
Conflicting classifications of pathogenicity
Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
Health Risk
RS1340148485
Conflicting classifications of pathogenicity
Joubert syndrome, Nephronophthisis, Meckel-Gruber syndrome
Health Risk
All Variants (892)
RSID Category Clinical Significance Conditions
RS2500956859 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501035965 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, CEP290-related disorder, Bardet-Biedl syndrome 14
RS2501038652 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501043274 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501043847 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501049333 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501054131 Health Risk Likely pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2501054222 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501098597 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501271113 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501271560 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501274238 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501328740 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501464922 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501475352 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501499274 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501502246 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501504626 Health Risk Likely pathogenic Retinal dystrophy, Retinal dystrophy
RS2501504852 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2501800454 Health Risk Likely pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2501802132 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS281865190 Health Risk Likely pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS367676646 Health Risk Likely pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS386834155 Health Risk Likely pathogenic Meckel syndrome, type 4, Meckel syndrome
RS386834156 Health Risk Likely pathogenic Meckel syndrome, type 4, Meckel syndrome
RS757210438 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS758193337 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS758878983 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Senior-Loken syndrome 6, Leber congenital amaurosis 10
RS763226787 Health Risk Likely pathogenic Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
RS764551108 Health Risk Likely pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS766670248 Health Risk Likely pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS766952056 Health Risk Likely pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS770015278 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS77818876 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS779409629 Health Risk Likely pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS779865400 Health Risk Likely pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS781670422 Health Risk Likely pathogenic Retinitis pigmentosa, Nephronophthisis, Joubert syndrome
RS786205620 Health Risk Likely pathogenic
RS797044604 Health Risk Likely pathogenic Leber congenital amaurosis 10, Bardet-Biedl syndrome, Meckel syndrome
RS878853361 Health Risk Likely pathogenic Retinal dystrophy, Retinal dystrophy
RS886039805 Health Risk Likely pathogenic Meckel-Gruber syndrome, Meckel syndrome, type 4
RS935130451 Health Risk Likely pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS951979448 Health Risk Likely pathogenic Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
RS1014354752 Health Risk Pathogenic Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
RS1027368517 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS1033594764 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS1057519165 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS1064793733 Health Risk Pathogenic
RS1158268529 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS1159120623 Health Risk Pathogenic Bardet-Biedl syndrome 14, Nephronophthisis, Meckel-Gruber syndrome
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