CEP290 Chromosome 12

Centrosomal protein 290
892 variants 892 Health Risk

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What This Gene Does
This gene encodes a protein with 13 putative coiled-coil domains, a region with homology to SMC chromosome segregation ATPases, six KID motifs, three tropomyosin homology domains and an ATP/GTP binding site motif A. The protein is localized to the centrosome and cilia and has sites for N-glycosylation, tyrosine sulfation, phosphorylation, N-myristoylation, and amidation. Mutations in this gene have been associated with Joubert syndrome and nephronophthisis and the presence of antibodies against this protein is associated with several forms of cancer. [provided by RefSeq, Jul 2008]
Gene Info
Gene Group
MKS complex
Locus Type
gene with protein product
Location
12q21.32
Ensembl
ENSG00000198707
Associated Conditions (61)
Nephronophthisis
Meckel-Gruber syndrome
Joubert syndrome
Senior-Loken syndrome 6
Joubert syndrome 5
Leber congenital amaurosis 10
Meckel syndrome
type 4
Bardet-Biedl syndrome 14
Leber congenital amaurosis
Hepatocellular carcinoma
Inborn genetic diseases
CEP290-related disorder
Intellectual disability
Retinal dystrophy
Retinitis pigmentosa
Kidney disorder
CEP290-related ciliopathy
Joubert syndrome 1
Atypical hemolytic-uremic syndrome
+41 more conditions
Key Variants
RS1036812157
Conflicting classifications of pathogenicity
Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
Health Risk
RS11104729
Conflicting classifications of pathogenicity
Bardet-Biedl syndrome 14, Joubert syndrome 5, Leber congenital amaurosis 10
Health Risk
RS1159465602
Conflicting classifications of pathogenicity
Senior-Loken syndrome 6, Meckel syndrome, type 4
Health Risk
RS1165909730
Conflicting classifications of pathogenicity
Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
Health Risk
RS117370446
Conflicting classifications of pathogenicity
Meckel syndrome, type 4, Bardet-Biedl syndrome 14
Health Risk
RS117852025
Conflicting classifications of pathogenicity
Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
Health Risk
RS11836796
Conflicting classifications of pathogenicity
Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
Health Risk
RS1200834763
Conflicting classifications of pathogenicity
Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
Health Risk
RS1213124542
Conflicting classifications of pathogenicity
Retinal dystrophy, CEP290-related disorder, Retinal dystrophy
Health Risk
RS1301659851
Conflicting classifications of pathogenicity
Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
Health Risk
RS1330745435
Conflicting classifications of pathogenicity
Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
Health Risk
RS1340148485
Conflicting classifications of pathogenicity
Joubert syndrome, Nephronophthisis, Meckel-Gruber syndrome
Health Risk
All Variants (892)
RSID Category Clinical Significance Conditions
RS2137868361 Health Risk Pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS2137903965 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2137917114 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2137919146 Health Risk Pathogenic Leber congenital amaurosis 10, Leber congenital amaurosis 10
RS2138000998 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138023519 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138083048 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138085855 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2138086329 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138086844 Health Risk Pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS2138093868 Health Risk Pathogenic Joubert syndrome, Nephronophthisis, Meckel-Gruber syndrome
RS2138093974 Health Risk Pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS2138215714 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2138215835 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138257533 Health Risk Pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS2138258864 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2138259100 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2138297703 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2138298697 Health Risk Pathogenic Leber congenital amaurosis 10, Leber congenital amaurosis 10
RS2499339388 Health Risk Pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2499339598 Health Risk Pathogenic Nephronophthisis, Meckel-Gruber syndrome, Joubert syndrome
RS2499426087 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499444567 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499445099 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499445529 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499470143 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499570339 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499571894 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499572404 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499617642 Health Risk Pathogenic Meckel-Gruber syndrome, Joubert syndrome, Nephronophthisis
RS2499619599 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2499619686 Health Risk Pathogenic Joubert syndrome, Nephronophthisis, Meckel-Gruber syndrome
RS2499620281 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499676199 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499740973 Health Risk Pathogenic Joubert syndrome, Nephronophthisis, Meckel-Gruber syndrome
RS2499741312 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499741922 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499745673 Health Risk Pathogenic CEP290-related disorder, CEP290-related disorder
RS2499745769 Health Risk Pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2499843752 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499853126 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499855740 Health Risk Pathogenic Bardet-Biedl syndrome 14, Bardet-Biedl syndrome 14
RS2499856690 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499858442 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499859881 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499860456 Health Risk Pathogenic Meckel-Gruber syndrome, Nephronophthisis, Joubert syndrome
RS2499907395 Health Risk Pathogenic Joubert syndrome, Meckel-Gruber syndrome, Nephronophthisis
RS2499910206 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499910412 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
RS2499911513 Health Risk Pathogenic Nephronophthisis, Joubert syndrome, Meckel-Gruber syndrome
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