CCDC40 Chromosome 17

Coiled-coil domain 40 molecular ruler complex subunit
162 variants 162 Health Risk

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What This Gene Does
This gene encodes a protein that is necessary for motile cilia function. It functions in correct left-right axis formation by regulating the assembly of the inner dynein arm and the dynein regulatory complexes, which control ciliary beat. Mutations in this gene cause ciliary dyskinesia type 15, a disorder due to defects in cilia motility. Alternative splicing results in multiple transcript variants. [provided by RefSeq, Aug 2011]
Gene Info
Gene Group
"Cilia and flagella associated|MicroRNA protein coding host genes"
Locus Type
gene with protein product
Location
17q25.3
Ensembl
ENSG00000141519
Associated Conditions (13)
Primary ciliary dyskinesia
Primary ciliary dyskinesia 15
CCDC40-related disorder
Male infertility
Usher syndrome
Thyroid cancer
nonmedullary
1
Heterotaxy
Primary ciliary dyskinesia 3
Kartagener syndrome
Combined immunodeficiency due to DOCK8 deficiency
Respiratory ciliopathies including non-CF bronchiectasis
Key Variants
RS115850223
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS117307093
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS117419007
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS138001923
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia
Health Risk
RS139435501
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, CCDC40-related disorder
Health Risk
RS141343307
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS1434924240
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, Primary ciliary dyskinesia 15
Health Risk
RS145013523
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS146360951
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
RS148674510
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, Primary ciliary dyskinesia 15
Health Risk
RS1489341724
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia
Health Risk
RS185157579
Conflicting classifications of pathogenicity
Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
Health Risk
All Variants (162)
RSID Category Clinical Significance Conditions
RS1336208372 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS1353073416 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS1363364769 Health Risk Pathogenic Heterotaxy, Heterotaxy
RS1418585908 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
RS145595957 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS1472033145 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS1487064371 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS1567819753 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS201223986 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2037236648 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2037491178 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2038617610 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2143577665 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2143733843 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2143735173 Health Risk Pathogenic
RS2143789412 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510283811 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510284153 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510284280 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510289393 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia 15
RS2510290432 Health Risk Pathogenic Primary ciliary dyskinesia 3, Primary ciliary dyskinesia 3
RS2510295858 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510295924 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia 15
RS2510315381 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510317115 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510324631 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS2510328737 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS367614851 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS370706991 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, CCDC40-related disorder
RS371595543 Health Risk Pathogenic Primary ciliary dyskinesia, CCDC40-related disorder, Primary ciliary dyskinesia 15
RS387907092 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, Primary ciliary dyskinesia 15
RS387907093 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, Primary ciliary dyskinesia 15
RS397515393 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, CCDC40-related disorder
RS587778819 Health Risk Pathogenic Primary ciliary dyskinesia 15, Primary ciliary dyskinesia, Kartagener syndrome
RS745993158 Health Risk Pathogenic Kartagener syndrome, Primary ciliary dyskinesia, Kartagener syndrome
RS747233125 Health Risk Pathogenic Primary ciliary dyskinesia, Combined immunodeficiency due to DOCK8 deficiency, Primary ciliary dyskinesia
RS747620444 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS750708201 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS751191119 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS754867753 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
RS755004291 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS757076408 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS761619279 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
RS764011276 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
RS764551914 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS773796940 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS775299709 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia 15, Primary ciliary dyskinesia
RS780516910 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS781507988 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
RS863224519 Health Risk Pathogenic Primary ciliary dyskinesia, Primary ciliary dyskinesia
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