AP4S1 Chromosome 14

Adaptor related protein complex 4 subunit sigma 1
24 variants 24 Health Risk

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What This Gene Does
This gene encodes a member of the adaptor complexes small subunit protein family. These proteins are components of the heterotetrameric adaptor protein complexes, which play important roles in the secretory and endocytic pathways by mediating vesicle formation and sorting of integral membrane proteins. The encoded protein is the small subunit of adaptor protein complex-4, which is associated with both clathrin- and nonclathrin-coated vesicles. Mutations in this gene are associated with spastic quadriplegic cerebral palsy-6. Alternatively spliced transcript variants encoding multiple isoforms have been observed for this gene, and a pseudogene of this gene is located on the long arm of chromosome 6. [provided by RefSeq, Dec 2011]
Gene Info
Gene Group
Adaptor related protein complex 4
Locus Type
gene with protein product
Location
14q12
Ensembl
ENSG00000100478
Associated Conditions (12)
Spastic paraplegia
Hereditary spastic paraplegia 52
Hereditary spastic paraplegia
Inborn genetic diseases
Thyroid cancer
nonmedullary
1
Neurodevelopmental disorder
APS41-related disorder
Intellectual disability
Spastic Paraplegia 52
AP4S1-related disorder
Key Variants
All Variants (24)
RSID Category Clinical Significance Conditions
RS147135554 Health Risk Conflicting classifications of pathogenicity Spastic paraplegia, Hereditary spastic paraplegia 52, Hereditary spastic paraplegia
RS200969079 Health Risk Conflicting classifications of pathogenicity Spastic paraplegia, Hereditary spastic paraplegia, Inborn genetic diseases
RS387906970 Health Risk Conflicting classifications of pathogenicity Hereditary spastic paraplegia 52, Spastic paraplegia, Spastic paraplegia
RS563687343 Health Risk Conflicting classifications of pathogenicity Hereditary spastic paraplegia 52, Hereditary spastic paraplegia 52
RS1335804396 Health Risk Likely pathogenic Inborn genetic diseases, Spastic paraplegia, Inborn genetic diseases
RS200033849 Health Risk Likely pathogenic Neurodevelopmental disorder, Spastic paraplegia, Neurodevelopmental disorder
RS2139067616 Health Risk Likely pathogenic Spastic paraplegia, Spastic paraplegia
RS2139067696 Health Risk Likely pathogenic Spastic paraplegia, Spastic paraplegia
RS2139098086 Health Risk Likely pathogenic Hereditary spastic paraplegia 52, Hereditary spastic paraplegia 52
RS2139569112 Health Risk Likely pathogenic Spastic paraplegia, Spastic paraplegia
RS377679827 Health Risk Likely pathogenic Hereditary spastic paraplegia 52, Hereditary spastic paraplegia 52
RS755820725 Health Risk Likely pathogenic Inborn genetic diseases, Spastic paraplegia, Inborn genetic diseases
RS758748011 Health Risk Likely pathogenic Hereditary spastic paraplegia 52, Spastic paraplegia, Hereditary spastic paraplegia 52
RS1566532837 Health Risk Pathogenic Spastic paraplegia, Spastic paraplegia
RS2139056017 Health Risk Pathogenic
RS2502388612 Health Risk Pathogenic Spastic paraplegia, Spastic paraplegia
RS2502522773 Health Risk Pathogenic Hereditary spastic paraplegia 52, Hereditary spastic paraplegia 52
RS568176223 Health Risk Pathogenic Inborn genetic diseases, Spastic paraplegia, Inborn genetic diseases
RS754944359 Health Risk Pathogenic Spastic paraplegia, Hereditary spastic paraplegia 52, Spastic paraplegia
RS777974629 Health Risk Pathogenic Spastic paraplegia, Spastic paraplegia
RS876661295 Health Risk Pathogenic Hereditary spastic paraplegia 52, APS41-related disorder, Intellectual disability
RS886041127 Health Risk Pathogenic Spastic paraplegia, Hereditary spastic paraplegia 52, Spastic paraplegia
RS185246578 Health Risk Pathogenic/Likely pathogenic Hereditary spastic paraplegia 52, Spastic paraplegia, Spastic Paraplegia 52
RS200440467 Health Risk Pathogenic/Likely pathogenic Hereditary spastic paraplegia 52, Spastic paraplegia, Intellectual disability
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